Distonia laríngea respiratória

Detalhes bibliográficos
Autor(a) principal: Lebl, Mariana Dantas Aumond [UNIFESP]
Data de Publicação: 2003
Outros Autores: De Biase, Noemi Grigoletto [UNIFESP], Silveira, Paula Angélica L. [UNIFESP], Pontes, Paulo Augusto de Lima [UNIFESP]
Tipo de documento: Artigo
Idioma: por
Título da fonte: Repositório Institucional da UNIFESP
Texto Completo: http://dx.doi.org/10.1590/S0034-72992003000500019
http://repositorio.unifesp.br/handle/11600/1866
Resumo: Laryngeal Breathing Dystonia (LBD) is a rare disorder characterized by inappropriate adduction of the true vocal cords during inspiration, resulting in stridor and dispnea. However, sometimes it is difficult to recognize the underlying etiology of the stridor, specially in emergencial situations, and LBD may be occasionally misdiagnosed, which makes this disease perhaps more frequent than it has been taught. The diagnosis is further supported by the finding of dystonic features and by exclusion of other causes of paradoxical vocal cord motion. There has been no satisfactory treatment for the disease. Botulinum toxin type A (Botox®) injection into the thyreoarytenoid muscle has been shown to be very effective, but only few cases have been reported. The authors describe the clinical presentation of Laryngeal Breathing Dystonia in two patients with complaints of stridor. Evaluation by laryngoscopy revealed paradoxical vocal cord motion and malacia of the epiglottis. Treatment was attempted by injection of Botox® in the adductor muscles. In this article the diagnostic approach of this disease is evaluated in accordance to the earliest concepts on laryngeal dystonias. Based on the classification system for laryngeal dystonias presented by Koufman and Blabock, the authors propose the recognition of a new subtype of DLR.
id UFSP_d2bccfb2e37991867f81079a2397a3e1
oai_identifier_str oai:repositorio.unifesp.br/:11600/1866
network_acronym_str UFSP
network_name_str Repositório Institucional da UNIFESP
repository_id_str 3465
spelling Distonia laríngea respiratóriaLaryngeal breathing dystoniadystoniavocal foldstridordistoniacorda vocalestridorLaryngeal Breathing Dystonia (LBD) is a rare disorder characterized by inappropriate adduction of the true vocal cords during inspiration, resulting in stridor and dispnea. However, sometimes it is difficult to recognize the underlying etiology of the stridor, specially in emergencial situations, and LBD may be occasionally misdiagnosed, which makes this disease perhaps more frequent than it has been taught. The diagnosis is further supported by the finding of dystonic features and by exclusion of other causes of paradoxical vocal cord motion. There has been no satisfactory treatment for the disease. Botulinum toxin type A (Botox®) injection into the thyreoarytenoid muscle has been shown to be very effective, but only few cases have been reported. The authors describe the clinical presentation of Laryngeal Breathing Dystonia in two patients with complaints of stridor. Evaluation by laryngoscopy revealed paradoxical vocal cord motion and malacia of the epiglottis. Treatment was attempted by injection of Botox® in the adductor muscles. In this article the diagnostic approach of this disease is evaluated in accordance to the earliest concepts on laryngeal dystonias. Based on the classification system for laryngeal dystonias presented by Koufman and Blabock, the authors propose the recognition of a new subtype of DLR.A distonia laríngea respiratória (DLR) é uma desordem rara caracterizada por espasmos da musculatura adutora das pregas vocais durante a fase inalatória da respiração, com manifestação clínica de dispnéia e estridor. O diagnóstico etiológico do estridor laríngeo, entretanto, nem sempre é fácil de ser realizado, principalmente em situações emergenciais, de forma que a DLR pode não ser diagnosticada, o que nos leva a supor ser mais freqüente do que usualmente é descrita. O diagnóstico da DRL requer primeiramente a realização de uma história médica e exames laringológico e neurológico apropriados, com ênfase na verificação da presença de características distônicas e na exclusão de outras etiologias causadoras de movimentos paradoxais de pregas vocais. Muitos tratamentos foram propostos para a DLR, mas nenhum deles apresentou resultados satisfatórios. O uso da Toxina Botulínica do tipo A (Botox®) no músculo tireoaritenoídeo tem oferecido melhoras admiráveis, apesar dos poucos casos descritos. Apresentamos dois casos clínicos de pacientes com DLR tratados com Botox® que apresentavam o fechamento glótico inspiratório causado tanto pelos espasmos anômalos dos músculos tireoaritenoídeos, como pela movimentação paradoxal da epiglote. Dentro da classificação proposta por Koufman e Blabock para as distonias laríngeas, inserimos um novo subtipo de DLR caracterizado pela presença de paroxismos de adução de estruturas glóticas e supraglóticas durante a respiração.Universidade Federal de São Paulo (UNIFESP) Escola Paulista de MedicinaUniversidade Federal de São Paulo (UNIFESP) Escola Paulista de Medicina Instituto da LaringeUniversidade Federal de São Paulo (UNIFESP) Escola Paulista de Medicina OtorrinolaringologiaUNIFESP, EPM, Instituto da LaringeUNIFESP, EPM, OtorrinolaringologiaSciELOABORL-CCF Associação Brasileira de Otorrinolaringologia e Cirurgia Cérvico-FacialUniversidade Federal de São Paulo (UNIFESP)Lebl, Mariana Dantas Aumond [UNIFESP]De Biase, Noemi Grigoletto [UNIFESP]Silveira, Paula Angélica L. [UNIFESP]Pontes, Paulo Augusto de Lima [UNIFESP]2015-06-14T13:30:09Z2015-06-14T13:30:09Z2003-10-01info:eu-repo/semantics/articleinfo:eu-repo/semantics/publishedVersion721-726application/pdfhttp://dx.doi.org/10.1590/S0034-72992003000500019Revista Brasileira de Otorrinolaringologia. ABORL-CCF Associação Brasileira de Otorrinolaringologia e Cirurgia Cérvico-Facial, v. 69, n. 5, p. 721-726, 2003.10.1590/S0034-72992003000500019S0034-72992003000500019.pdf0034-7299S0034-72992003000500019http://repositorio.unifesp.br/handle/11600/1866porRevista Brasileira de Otorrinolaringologiainfo:eu-repo/semantics/openAccessreponame:Repositório Institucional da UNIFESPinstname:Universidade Federal de São Paulo (UNIFESP)instacron:UNIFESP2024-08-05T18:58:54Zoai:repositorio.unifesp.br/:11600/1866Repositório InstitucionalPUBhttp://www.repositorio.unifesp.br/oai/requestbiblioteca.csp@unifesp.bropendoar:34652024-08-05T18:58:54Repositório Institucional da UNIFESP - Universidade Federal de São Paulo (UNIFESP)false
dc.title.none.fl_str_mv Distonia laríngea respiratória
Laryngeal breathing dystonia
title Distonia laríngea respiratória
spellingShingle Distonia laríngea respiratória
Lebl, Mariana Dantas Aumond [UNIFESP]
dystonia
vocal fold
stridor
distonia
corda vocal
estridor
title_short Distonia laríngea respiratória
title_full Distonia laríngea respiratória
title_fullStr Distonia laríngea respiratória
title_full_unstemmed Distonia laríngea respiratória
title_sort Distonia laríngea respiratória
author Lebl, Mariana Dantas Aumond [UNIFESP]
author_facet Lebl, Mariana Dantas Aumond [UNIFESP]
De Biase, Noemi Grigoletto [UNIFESP]
Silveira, Paula Angélica L. [UNIFESP]
Pontes, Paulo Augusto de Lima [UNIFESP]
author_role author
author2 De Biase, Noemi Grigoletto [UNIFESP]
Silveira, Paula Angélica L. [UNIFESP]
Pontes, Paulo Augusto de Lima [UNIFESP]
author2_role author
author
author
dc.contributor.none.fl_str_mv Universidade Federal de São Paulo (UNIFESP)
dc.contributor.author.fl_str_mv Lebl, Mariana Dantas Aumond [UNIFESP]
De Biase, Noemi Grigoletto [UNIFESP]
Silveira, Paula Angélica L. [UNIFESP]
Pontes, Paulo Augusto de Lima [UNIFESP]
dc.subject.por.fl_str_mv dystonia
vocal fold
stridor
distonia
corda vocal
estridor
topic dystonia
vocal fold
stridor
distonia
corda vocal
estridor
description Laryngeal Breathing Dystonia (LBD) is a rare disorder characterized by inappropriate adduction of the true vocal cords during inspiration, resulting in stridor and dispnea. However, sometimes it is difficult to recognize the underlying etiology of the stridor, specially in emergencial situations, and LBD may be occasionally misdiagnosed, which makes this disease perhaps more frequent than it has been taught. The diagnosis is further supported by the finding of dystonic features and by exclusion of other causes of paradoxical vocal cord motion. There has been no satisfactory treatment for the disease. Botulinum toxin type A (Botox®) injection into the thyreoarytenoid muscle has been shown to be very effective, but only few cases have been reported. The authors describe the clinical presentation of Laryngeal Breathing Dystonia in two patients with complaints of stridor. Evaluation by laryngoscopy revealed paradoxical vocal cord motion and malacia of the epiglottis. Treatment was attempted by injection of Botox® in the adductor muscles. In this article the diagnostic approach of this disease is evaluated in accordance to the earliest concepts on laryngeal dystonias. Based on the classification system for laryngeal dystonias presented by Koufman and Blabock, the authors propose the recognition of a new subtype of DLR.
publishDate 2003
dc.date.none.fl_str_mv 2003-10-01
2015-06-14T13:30:09Z
2015-06-14T13:30:09Z
dc.type.driver.fl_str_mv info:eu-repo/semantics/article
dc.type.status.fl_str_mv info:eu-repo/semantics/publishedVersion
format article
status_str publishedVersion
dc.identifier.uri.fl_str_mv http://dx.doi.org/10.1590/S0034-72992003000500019
Revista Brasileira de Otorrinolaringologia. ABORL-CCF Associação Brasileira de Otorrinolaringologia e Cirurgia Cérvico-Facial, v. 69, n. 5, p. 721-726, 2003.
10.1590/S0034-72992003000500019
S0034-72992003000500019.pdf
0034-7299
S0034-72992003000500019
http://repositorio.unifesp.br/handle/11600/1866
url http://dx.doi.org/10.1590/S0034-72992003000500019
http://repositorio.unifesp.br/handle/11600/1866
identifier_str_mv Revista Brasileira de Otorrinolaringologia. ABORL-CCF Associação Brasileira de Otorrinolaringologia e Cirurgia Cérvico-Facial, v. 69, n. 5, p. 721-726, 2003.
10.1590/S0034-72992003000500019
S0034-72992003000500019.pdf
0034-7299
S0034-72992003000500019
dc.language.iso.fl_str_mv por
language por
dc.relation.none.fl_str_mv Revista Brasileira de Otorrinolaringologia
dc.rights.driver.fl_str_mv info:eu-repo/semantics/openAccess
eu_rights_str_mv openAccess
dc.format.none.fl_str_mv 721-726
application/pdf
dc.publisher.none.fl_str_mv ABORL-CCF Associação Brasileira de Otorrinolaringologia e Cirurgia Cérvico-Facial
publisher.none.fl_str_mv ABORL-CCF Associação Brasileira de Otorrinolaringologia e Cirurgia Cérvico-Facial
dc.source.none.fl_str_mv reponame:Repositório Institucional da UNIFESP
instname:Universidade Federal de São Paulo (UNIFESP)
instacron:UNIFESP
instname_str Universidade Federal de São Paulo (UNIFESP)
instacron_str UNIFESP
institution UNIFESP
reponame_str Repositório Institucional da UNIFESP
collection Repositório Institucional da UNIFESP
repository.name.fl_str_mv Repositório Institucional da UNIFESP - Universidade Federal de São Paulo (UNIFESP)
repository.mail.fl_str_mv biblioteca.csp@unifesp.br
_version_ 1814268266958290944